Publication:
PRO136ALA CTLA4 Mutation

No Thumbnail Available

Date

2017-06-07

Published Version

Published Version

Journal Title

Journal ISSN

Volume Title

Publisher

The Harvard community has made this article openly available. Please share how this access benefits you.

Research Projects

Organizational Units

Journal Issue

Citation

Palmer, Cody. 2017. PRO136ALA CTLA4 Mutation. Master's thesis, Harvard Medical School.

Research Data

Abstract

Cytotoxic T lymphocyte antigen–4 (CTLA-4) is an inhibitory receptor involved in the regulation of immune responses. Deficiency of Ctla4 in mice causes fatal multiorgan lymphocytic infiltration. We identified a heterozygous, missense c.406C>G, p.P136A mutation in CTLA4 in a CVID patient. This mutation is within the binding motif of CTLA-4 and is predicted to interfere with ligand binding. To test whether this mutation is causal in the phenotype of the patient, we will use CRISPR/Cas9-mediated genome editing to clone the mutation into a regulatory T cell-like cell line and use the edited cell line for functional studies.

Description

Other Available Sources

Keywords

Terms of Use

This article is made available under the terms and conditions applicable to Other Posted Material (LAA), as set forth at Terms of Service

Endorsement

Review

Supplemented By

Referenced By

Related Stories